Psychological well-being in parents of children with Angelman, Cornelia de Lange and Cri du Chat syndromes.

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Psychological well-being in parents of children with Angelman, Cornelia de Lange and Cri du Chat syndromes. / Griffith, Gemma; Hastings, RP; Oliver, Christopher; Howlin, P; Moss, Joanna; Petty, Jane; Tunnicliffe, Penelope.

In: Journal of Intellectual Disability Research, Vol. 55, No. 4, 01.04.2011, p. 397-410.

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@article{46e221aec2f94704bbabdb1faeb8cf93,
title = "Psychological well-being in parents of children with Angelman, Cornelia de Lange and Cri du Chat syndromes.",
abstract = "Background  The current study focuses on mothers and fathers of children with three rare genetic syndromes that are relatively unexplored in terms of family experience: Angelman syndrome, Cornelia de Lange syndrome and Cri du Chat syndrome. Method  Parents of children with Angelman syndrome (n = 15), Cornelia de Lange syndrome (n = 16) and Cri du Chat syndrome (n = 18), and a matched comparison group of parents of children with autism and intellectual disabilities (n = 20) completed questionnaires on both psychological distress (stress, anxiety, depression) and positive psychological functioning. Results  Parents of children with Angelman syndrome consistently reported the highest levels of psychological distress, and parents of children with Cornelia de Lange syndrome the lowest, with parents of children with Cri du Chat syndrome and autism scoring between these two. Positive psychological functioning was similar across the four aetiology groups. Conclusions  Parents of children with rare genetic syndromes are at risk for high levels of stress and mental health problems. Methodological issues and the practical applications of these results are discussed.",
author = "Gemma Griffith and RP Hastings and Christopher Oliver and P Howlin and Joanna Moss and Jane Petty and Penelope Tunnicliffe",
year = "2011",
month = apr,
day = "1",
doi = "10.1111/j.1365-2788.2011.01386.x",
language = "English",
volume = "55",
pages = "397--410",
journal = "Journal of Intellectual Disability Research",
issn = "0964-2633",
publisher = "Wiley",
number = "4",

}

RIS

TY - JOUR

T1 - Psychological well-being in parents of children with Angelman, Cornelia de Lange and Cri du Chat syndromes.

AU - Griffith, Gemma

AU - Hastings, RP

AU - Oliver, Christopher

AU - Howlin, P

AU - Moss, Joanna

AU - Petty, Jane

AU - Tunnicliffe, Penelope

PY - 2011/4/1

Y1 - 2011/4/1

N2 - Background  The current study focuses on mothers and fathers of children with three rare genetic syndromes that are relatively unexplored in terms of family experience: Angelman syndrome, Cornelia de Lange syndrome and Cri du Chat syndrome. Method  Parents of children with Angelman syndrome (n = 15), Cornelia de Lange syndrome (n = 16) and Cri du Chat syndrome (n = 18), and a matched comparison group of parents of children with autism and intellectual disabilities (n = 20) completed questionnaires on both psychological distress (stress, anxiety, depression) and positive psychological functioning. Results  Parents of children with Angelman syndrome consistently reported the highest levels of psychological distress, and parents of children with Cornelia de Lange syndrome the lowest, with parents of children with Cri du Chat syndrome and autism scoring between these two. Positive psychological functioning was similar across the four aetiology groups. Conclusions  Parents of children with rare genetic syndromes are at risk for high levels of stress and mental health problems. Methodological issues and the practical applications of these results are discussed.

AB - Background  The current study focuses on mothers and fathers of children with three rare genetic syndromes that are relatively unexplored in terms of family experience: Angelman syndrome, Cornelia de Lange syndrome and Cri du Chat syndrome. Method  Parents of children with Angelman syndrome (n = 15), Cornelia de Lange syndrome (n = 16) and Cri du Chat syndrome (n = 18), and a matched comparison group of parents of children with autism and intellectual disabilities (n = 20) completed questionnaires on both psychological distress (stress, anxiety, depression) and positive psychological functioning. Results  Parents of children with Angelman syndrome consistently reported the highest levels of psychological distress, and parents of children with Cornelia de Lange syndrome the lowest, with parents of children with Cri du Chat syndrome and autism scoring between these two. Positive psychological functioning was similar across the four aetiology groups. Conclusions  Parents of children with rare genetic syndromes are at risk for high levels of stress and mental health problems. Methodological issues and the practical applications of these results are discussed.

U2 - 10.1111/j.1365-2788.2011.01386.x

DO - 10.1111/j.1365-2788.2011.01386.x

M3 - Article

C2 - 21323782

VL - 55

SP - 397

EP - 410

JO - Journal of Intellectual Disability Research

JF - Journal of Intellectual Disability Research

SN - 0964-2633

IS - 4

ER -